Cardiac amyloidosis in African Americans: comparison of clinical and laboratory features of transthyretin V122I amyloidosis and immunoglobulin light chain amyloidosis

Am Heart J. 2009 Oct;158(4):607-14. doi: 10.1016/j.ahj.2009.08.006.

Abstract

Background: Transthyretin (TTR) mutations known to cause cardiac amyloidosis include V122I, found almost exclusively in African Americans at a prevalence of 3-3.9%. This retrospective study describes TTR V122I-associated cardiac amyloid disease (ATTR) in a major amyloid referral clinic population.

Methods: Self-identified African Americans with amyloidosis (n = 156) were screened for TTR V122I by serum isoelectric focusing; mutant TTR was confirmed by DNA sequencing or mass spectrometry. Cardiac findings in ATTR V122I and immunoglobulin light chain (AL) amyloidoses were compared.

Results: TTR V122I was identified in 36/156 (23.1%) of evaluated patients and included 5 homozygotes; the allele frequency was 0.013. One compound heterozygote (F44L/V122I) and 4 patients who had AL and the mutant TTR allele were characterized. In patients negative for V122I, AL was the most frequent diagnosis (86/120). Cardiomyopathy was present in 100% of patients with ATTR and 84% of patients with AL (P = .01). In patients with dominant cardiac involvement, better survival occurred in ATTR (n = 30) compared to AL (n = 31), (27 vs 5 months, P < .01) although the mean age in ATTR was higher (70.3 vs 56.2 years, P < .01). Congestive heart failure symptoms and electrocardiographic findings were similar in ATTR and AL, but significant differences in echocardiographic measurements were observed.

Conclusions: ATTR V122I and AL are equally prevalent as the cause of cardiomyopathy in African Americans referred for a diagnosis of amyloidosis. Available therapy for AL underscores the need for early and accurate determination of amyloid type.

Publication types

  • Comparative Study

MeSH terms

  • Aged
  • Alleles
  • Amyloidosis / ethnology*
  • Amyloidosis / genetics
  • Amyloidosis / metabolism
  • Black or African American*
  • Cardiomyopathies / ethnology*
  • Cardiomyopathies / genetics
  • Cardiomyopathies / metabolism
  • DNA / genetics*
  • Female
  • Follow-Up Studies
  • Gene Frequency
  • Humans
  • Immunoglobulin Light Chains / blood*
  • Immunohistochemistry
  • Male
  • Mass Spectrometry
  • Massachusetts / epidemiology
  • Middle Aged
  • Mutation*
  • Prealbumin / genetics*
  • Prealbumin / metabolism
  • Prevalence
  • Prognosis
  • Retrospective Studies
  • Sequence Analysis, DNA

Substances

  • Immunoglobulin Light Chains
  • Prealbumin
  • DNA