Isolated recurrent pleuritis revealing familial mediterranean Fever in adulthood

Respiration. 2010;79(6):508-10. doi: 10.1159/000272314. Epub 2009 Dec 24.

Abstract

Familial Mediterranean fever (FMF) is a genetic autoinflammatory disease especially affecting populations of Mediterranean origin with an autosomal recessive inheritance. The cardinal manifestations consist of short febrile and painful attacks of peritonitis, arthritis and pleuritis developing during childhood. We report the case of a 26-year-old man of Tunisian descent who had febrile episodes of right-sided pleuritis without any extrathoracic complaints. Disappearance of attacks with one dose of colchicine (1 mg/day) strengthened the presumptive diagnosis of atypical FMF, which was further confirmed by genetic testing identifying the homozygous mutation M694I/M694I of the MEFV gene.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Colchicine / therapeutic use
  • Familial Mediterranean Fever / complications*
  • Familial Mediterranean Fever / diagnosis
  • Humans
  • Male
  • Pleurisy / diagnostic imaging
  • Pleurisy / drug therapy
  • Pleurisy / etiology*
  • Radiography
  • Recurrence

Substances

  • Colchicine