Progressive cerebral white matter involvement in a patient with Congenital Cataracts Facial Dysmorphisms Neuropathy (CCFDN)

Neuromuscul Disord. 2010 May;20(5):343-5. doi: 10.1016/j.nmd.2010.03.003. Epub 2010 Mar 28.

Abstract

Congenital Cataracts with Facial Dysmorphisms and Neuropathy (CCFDN) is a complex autosomal recessive disorder characterized by bilateral congenital cataracts, developmental delay, peripheral; hypo-demyelinating neuropathy, mild facial dysmorphisms, and other rare signs. Cerebral and spinal cord atrophy is the main neuroimaging finding but other less common abnormalities have been previously described. We describe progressive focal lesions of supratentorial white matter in a 10-year-old boy affected by CCFDN. Other etiologies have been excluded and these lesions can be considered a new finding of the disease. We discuss a possible demyelinating mechanism affecting both peripheral and central myelin.

Publication types

  • Case Reports

MeSH terms

  • Cataract* / complications
  • Cataract* / congenital
  • Cataract* / pathology
  • Cerebral Cortex / pathology*
  • Child
  • Face / abnormalities*
  • Facial Nerve Diseases* / complications
  • Facial Nerve Diseases* / congenital
  • Facial Nerve Diseases* / pathology
  • Humans
  • Magnetic Resonance Imaging / methods
  • Male
  • Nerve Fibers, Myelinated / pathology*