Prospective assessment of health-related quality of life in pediatric patients with beta-thalassemia following hematopoietic stem cell transplantation

Biol Blood Marrow Transplant. 2011 Jun;17(6):861-6. doi: 10.1016/j.bbmt.2010.09.011. Epub 2010 Sep 24.

Abstract

Although hematopoietic stem cell transplantation (HSCT) has been widely used to treat pediatric patients with beta-thalassemia major, evidence showing whether this treatment improves health-related quality of life (HRQoL) is lacking. We used child-self and parent-proxy reports to prospectively evaluate HRQoL in 28 children with beta-thalassemia from Middle Eastern countries who underwent allogeneic HSCT in Italy. The PedsQL 4.0 Generic Core Scales were administered to patients and their parents 1 month before and 3, 6, and 18 months after transplantation. Two-year overall survival, thalassemia-free survival, mortality, and rejection were 89.3%, 78.6%, 10.9% and 14.3%, respectively. The cumulative incidence of acute and chronic graft-versus-host disease (GVHD) was 36% and 18%, respectively. Physical functioning declined significantly from baseline to 3 months after HSCT (median PedsQL score, 81.3 vs 62.5; P = .02), but then increased significantly up to 18 months after HSCT (median score, 93.7; P = .04). Agreement between child-self and parent-proxy ratings was high. Chronic GVHD was the most significant factor associated with lower HRQoL scores over time (P = .02). The child-self and parent-proxy reports showed improved HRQoL in the children with beta-thalassemia after HSCT. Overall, our study provides preliminary evidence-based data to further support clinical decision making in this area.

MeSH terms

  • Activities of Daily Living
  • Adolescent
  • Child
  • Child, Preschool
  • Female
  • Graft vs Host Disease / mortality
  • Graft vs Host Disease / pathology
  • Graft vs Host Disease / psychology*
  • Health Status
  • Hematopoietic Stem Cell Transplantation / mortality
  • Hematopoietic Stem Cell Transplantation / psychology*
  • Humans
  • Incidence
  • Italy
  • Male
  • Middle East
  • Parents
  • Pediatrics
  • Prospective Studies
  • Quality of Life / psychology*
  • Sickness Impact Profile
  • Surveys and Questionnaires
  • Survival Analysis
  • beta-Thalassemia / mortality
  • beta-Thalassemia / pathology
  • beta-Thalassemia / psychology*
  • beta-Thalassemia / therapy