Retinal nerve fiber thickness measurements in choroideremia patients with spectral-domain optical coherence tomography

Ophthalmic Genet. 2011 Jun;32(2):101-6. doi: 10.3109/13816810.2010.544364. Epub 2011 Jan 26.

Abstract

Purpose: To evaluate the presence of peripapillary retinal nerve fiber layer (RNFL) defects in patients with choroideremia by using spectral-domain optical coherence tomography (SD-OCT).

Methods: Twenty-nine eyes of 16 patients with choroideremia underwent peripapillary RNFL thickness measurements by using SD-OCT.

Results: The mean (±SD) age of the study population was 44.0 ± 16.0 years (range, 13-63 years). Thirteen eyes (45%) showed a thinning of the peripapillary RNFL in at least 1 quadrant in either 1 or both eyes. Thinning was most commonly found in the superior (13 eyes) and inferior (10 eyes) quadrants. Twenty-one eyes (72%) showed a thickening of the peripapillary RNFL in at least 1 quadrant in either 1 or both eyes. Of these 21 eyes, all had thickening in the temporal quadrant. Additionally, 2 eyes in each of the other 3 quadrants were found to be abnormally thick.

Conclusion: Our study demonstrated the presence of defects in the peripapillary RNFL thickness in patients with choroideremia by using SD-OCT. It would be clinically prudent that choroideremia patients considered for various treatment options be considered for RNFL thickness measurements.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Choroideremia / diagnosis*
  • Choroideremia / genetics
  • Female
  • Humans
  • Male
  • Middle Aged
  • Mutation, Missense
  • Nerve Fibers / pathology*
  • Optic Nerve / pathology*
  • Optic Nerve Diseases / diagnosis*
  • Prospective Studies
  • Retinal Ganglion Cells / pathology*
  • Tomography, Optical Coherence
  • Visual Acuity / physiology