New homozygous SPINK5 mutation, p.Gln333X, in a Turkish pedigree with Netherton syndrome

Clin Exp Dermatol. 2011 Jun;36(4):412-5. doi: 10.1111/j.1365-2230.2010.03976.x. Epub 2010 Dec 24.

Abstract

Netherton syndrome (NS) is a rare autosomal recessive genodermatosis caused by loss-of-function mutations in the SPINK5 gene. The clinical features include congenital ichthyosis, trichorrhexis invaginata and atopy. In this study, we report a new homozygous SPINK5 mutation, p.Gln333X, responsible for NS in affected members of two closely related Turkish families, and provide an overview of the genotype-phenotype correlation in this condition.

Publication types

  • Case Reports

MeSH terms

  • Consanguinity
  • Female
  • Genetic Association Studies
  • Homozygote
  • Humans
  • Male
  • Mutation / genetics*
  • Netherton Syndrome / genetics*
  • Pedigree
  • Proteinase Inhibitory Proteins, Secretory / genetics*
  • Serine Peptidase Inhibitor Kazal-Type 5
  • Turkey

Substances

  • Proteinase Inhibitory Proteins, Secretory
  • SPINK5 protein, human
  • Serine Peptidase Inhibitor Kazal-Type 5