A novel 5-bp deletion in Clarin 1 in a family with Usher syndrome

Ophthalmic Genet. 2011 Nov;32(4):245-9. doi: 10.3109/13816810.2011.587083. Epub 2011 Jun 15.

Abstract

Background: To identify the genetic defect in a Lebanese family with two sibs diagnosed with Usher Syndrome.

Materials and methods: Exome capture and sequencing were performed on DNA from one affected member using Agilent in solution bead capture, followed by Illumina sequencing.

Results: This analysis revealed the presence of a novel homozygous 5-bp deletion, in Clarin 1 (CLRN1), a known gene responsible for Usher syndrome type III. The deletion is inherited from both parents and segregates with the disease phenotype in the family. The 5-bp deletion, c.301_305delGTCAT, p.Val101SerfsX27, is predicted to result in a frameshift and protein truncation after 27 amino acids. Sequencing all the coding regions of the CLRN1 gene in the proband did not reveal any other mutation or variant.

Conclusion: Here we describe a novel deletion in CLRN1. Our data support previously reported intra familial variability in the clinical features of Usher syndrome type I and III.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Base Pairing
  • Child
  • DNA / genetics*
  • DNA Mutational Analysis
  • Exome / genetics
  • Frameshift Mutation / genetics
  • Humans
  • Male
  • Membrane Proteins / genetics*
  • Sequence Analysis, DNA
  • Sequence Deletion / genetics*
  • Siblings
  • Usher Syndromes / genetics*

Substances

  • CLRN1 protein, human
  • Membrane Proteins
  • DNA