Identification of mutations causing hereditary tyrosinemia type I in patients of Middle Eastern origin

Mol Genet Metab. 2011 Dec;104(4):688-90. doi: 10.1016/j.ymgme.2011.06.019. Epub 2011 Jun 30.

Abstract

Hereditary Tyrosinemia Type 1 (HT1) is an autosomal recessive disorder resulting from a deficiency of fumarylacetoacetase caused by mutations in the fumarylacetoacetate hydrolase (FAH) gene. We detected 11 novel and 6 previously described pathogenic mutations in a cohort of 43 patients originating from the Middle East with the acute form HT1. All of the mutations were homozygous and we did not find the presence of a "founder mutation".

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Case-Control Studies
  • Consanguinity
  • DNA Mutational Analysis
  • Egypt
  • Genetic Association Studies
  • Heredity
  • Homozygote
  • Hydrolases / genetics*
  • Iran
  • Mutation*
  • Saudi Arabia
  • Tyrosinemias / genetics*

Substances

  • Hydrolases
  • fumarylacetoacetase