Transgene expression in the striatum following intracerebral injections of DNA nanoparticles encoding for human glial cell line-derived neurotrophic factor

Neuroscience. 2011 Oct 27:194:220-6. doi: 10.1016/j.neuroscience.2011.07.072. Epub 2011 Aug 4.

Abstract

A goal of our studies is to develop a potential therapeutic for Parkinson's disease (PD) by a human glial cell line-derived neurotrophic factor (hGDNF) expression plasmid administered to the rat striatum as a compacted DNA nanoparticle (DNP) and which will generate long-term hGDNF expression at biologically active levels. In the present study, we used a DNA plasmid encoding for hGDNF and a polyubiquitin C (UbC) promoter that was previously shown to have activity in both neurons and glia, but primarily in glia. A two-fold improvement was observed at the highest plasmid dose when using hGDNF DNA incorporating sequences found in RNA splice variant 1 compared with splice variant 2; of note, the splice variant 2 sequence is used in most preclinical studies. This optimized expression cassette design includes flanking scaffold matrix attachment elements (S/MARs) as well as a CpG-depleted prokaryotic domain and, where possible, eukaryotic elements. Stable long-term GDNF activity at levels 300-400% higher than baseline was observed following a single intracerebral injection. In a previous study, DNP plasmids encoding for reporter genes had been successful in generating long-term reporter transgene activity in the striatum (>365 days) and in this study produced sustained GDNF activity at the longest assessed time point (6 months).

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Animals
  • Brain Chemistry / genetics*
  • Corpus Striatum / metabolism*
  • DNA / administration & dosage*
  • Disease Models, Animal
  • Drug Delivery Systems / methods
  • Gene Expression Regulation / genetics
  • Genetic Therapy / methods*
  • Glial Cell Line-Derived Neurotrophic Factor / administration & dosage
  • Glial Cell Line-Derived Neurotrophic Factor / genetics*
  • Humans
  • Male
  • Microinjections / methods
  • Nanoparticles / administration & dosage*
  • Nanoparticles / therapeutic use
  • Parkinsonian Disorders / genetics
  • Parkinsonian Disorders / metabolism
  • Parkinsonian Disorders / therapy
  • Primary Cell Culture
  • Rats
  • Rats, Sprague-Dawley

Substances

  • Glial Cell Line-Derived Neurotrophic Factor
  • DNA