Persistent fetal sinus bradycardia associated with maternal anti-SSA/Ro and anti-SSB/La antibodies

J Rheumatol. 2011 Dec;38(12):2682-5. doi: 10.3899/jrheum.110720. Epub 2011 Nov 15.

Abstract

Objective: To study the clinical course and outcome of fetal sinus bradycardia (SB) due to maternal antibody-induced sinus node dysfunction.

Methods: We reviewed the maternal, prenatal, and postnatal findings of fetuses with SB associated with elevated maternal anti-SSA/Ro and anti-SSB/La antibodies.

Results: Of the 6 cases diagnosed prenatally, 3 had isolated SB persisting after birth and had a good prognosis. Three fetuses with SB and severe myocardial involvement (congenital complete heart block and/or endocardial fibroelastosis) succumbed in utero in spite of treatment. Postmortem histopathology in 1 fetus showed inflammatory destruction of the sinus and atrioventricular nodes. SB was detected incidentally in a 7-year-old girl. She had intermittent heart block with progressive sinus arrest requiring permanent pacemaker.

Conclusion: Fetal SB associated with maternal autoantibodies may persist in childhood, with a good prognosis in the absence of widespread cardiac involvement.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Antibodies, Antinuclear / immunology*
  • Autoantigens / immunology
  • Bradycardia / immunology*
  • Bradycardia / physiopathology
  • Child
  • Child, Preschool
  • Female
  • Fetus / immunology*
  • Fetus / pathology
  • Fetus / physiopathology*
  • Heart Block / congenital
  • Heart Block / immunology
  • Heart Block / physiopathology
  • Humans
  • Pregnancy / immunology*
  • Ribonucleoproteins / immunology
  • SS-B Antigen
  • Sick Sinus Syndrome / immunology*
  • Sick Sinus Syndrome / physiopathology

Substances

  • Antibodies, Antinuclear
  • Autoantigens
  • Ribonucleoproteins
  • SS-A antibodies
  • SS-A antigen
  • SS-B antibodies

Supplementary concepts

  • Congenital heart block