A cytogenetic analysis of 2 cases of phosphaturic mesenchymal tumor of mixed connective tissue type

Hum Pathol. 2012 Aug;43(8):1334-8. doi: 10.1016/j.humpath.2011.11.020. Epub 2012 Apr 11.

Abstract

Phosphaturic mesenchymal tumor of mixed connective tissue type is a rare, histologically distinctive mesenchymal neoplasm associated with tumor-induced osteomalacia resulting from production of the phosphaturic hormone fibroblast growth factor 23. Because of its rarity, specific genetic alterations that contribute to the pathogenesis of these tumors have yet to be elucidated. Herein, we report the abnormal karyotypes from 2 cases of confirmed phosphaturic mesenchymal tumor of mixed connective tissue type. G-banded analysis demonstrated the first tumor to have a karyotype of 46,Y,t(X;3;14)(q13;p25;q21)[15]/46XY[5], and the second tumor to have a karyotype of 46, XY,add(2)(q31),add(4)(q31.1)[2]/92,slx2[3]/46,sl,der(2)t(2;4)(q14.2;p14),der(4)t(2;4)(q14.2;p14),add(4)(q31.1)[10]/46,sdl,add(13)(q34)[4]/92,sdl2x2[1]. These represent what is, to our knowledge, the first examples of abnormal karyotypes obtained from phosphaturic mesenchymal tumor of mixed connective tissue type.

Publication types

  • Case Reports

MeSH terms

  • Abnormal Karyotype
  • Humans
  • Hypophosphatemia / etiology
  • Hypophosphatemia / genetics
  • Hypophosphatemia / pathology
  • Male
  • Mesenchymoma / complications
  • Mesenchymoma / genetics*
  • Mesenchymoma / pathology
  • Middle Aged
  • Neoplasms, Connective Tissue / etiology
  • Neoplasms, Connective Tissue / genetics*
  • Neoplasms, Connective Tissue / pathology
  • Osteomalacia / etiology
  • Osteomalacia / genetics*
  • Osteomalacia / pathology
  • Paraneoplastic Syndromes

Supplementary concepts

  • Oncogenic osteomalacia