Simplified gyral pattern with cerebellar hypoplasia in Sedaghatian type spondylometaphyseal dysplasia: a clinical report and review of the literature

Am J Med Genet A. 2012 Jun;158A(6):1400-5. doi: 10.1002/ajmg.a.35306. Epub 2012 Apr 23.

Abstract

We report on a patient with Sedaghatian type spondylometaphyseal dysplasia (SSMD) who presented with metaphyseal dysplasia, congenital atrioventricular block, simplified gyral pattern, hypogenesis of corpus callosum, and severe cerebellar hypoplasia. We want to emphasize that in this rare congenital lethal skeletal dysplasia with unknown etiology, central nervous system malformations might be a major component of the disorder and should be evaluated in detail to possibly uncover the underlying pathophysiology.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Brain / pathology
  • Cerebellum / abnormalities*
  • Fatal Outcome
  • Humans
  • Infant
  • Infant, Newborn
  • Male
  • Neuroimaging
  • Osteochondrodysplasias / complications
  • Osteochondrodysplasias / diagnosis*

Supplementary concepts

  • Spondylometaphyseal dysplasia, Sedaghatian type