COL4A1-related disease: raised creatine kinase and cerebral calcification as useful pointers

Neuropediatrics. 2012 Oct;43(5):283-8. doi: 10.1055/s-0032-1325116. Epub 2012 Aug 29.

Abstract

Background: Mutations in COL4A1 are responsible for a spectrum of clinical phenotypes characterized by neurological, ocular, and renal involvement. Neurological features are the most prominent but as such are rather nonspecific.

Case presentation: Here, we report three new cases that, like five patients we previously described, show the novel common finding of raised creatine kinase (CK) concentration.

Conclusion: Raised CK concentration, in addition to intracranial calcification, is to be considered another useful pointer to a final diagnosis of COL4A1-related disease.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Adult
  • Brain Diseases / genetics*
  • Brain Diseases / metabolism*
  • Brain Diseases / pathology
  • Calcinosis / etiology*
  • Calcinosis / genetics
  • Cerebral Cortex / pathology
  • Child
  • Child, Preschool
  • Collagen Type IV / genetics*
  • Creatine Kinase / metabolism*
  • Female
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Middle Aged
  • Mutation / genetics*
  • Nerve Fibers, Myelinated / pathology

Substances

  • COL4A1 protein, human
  • Collagen Type IV
  • Creatine Kinase