Tumefactive demyelinating lesions during etanercept treatment requiring decompressive hemicraniectomy

Mult Scler. 2013 May;19(6):820-3. doi: 10.1177/1352458512461969. Epub 2012 Oct 15.

Abstract

Tumor necrosis factor alpha (TNF-α) is a pro-inflammatory and immunoregulatory cytokine involved in the pathogenesis of several autoimmune disorders. Etanercept, a TNF-α antagonist (anti-TNF-α) acting as a soluble TNF-α receptor, has been associated with neurological demyelinating disorders. This paper aims to report an unusual case showing tumefactive central nervous system (CNS) inflammatory demyelination in a patient in the course of TNF -α antagonist therapy, requiring decompressive hemicraniectomy. This report is based on magnetic resonance imaging (MRI) findings and histology. A biopsy confirmed the inflammatory demyelinating nature of the lesions. The clinical presentation is unusual due to the severity of the disease process, requiring decompressive hemicraniotomy with a clinically favorable outcome.

Keywords: CNS demyelinating disease; Marburg’s variant; etanercept; multiple sclerosis.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Biopsy
  • Decompressive Craniectomy / methods*
  • Demyelinating Diseases / chemically induced
  • Demyelinating Diseases / diagnosis
  • Demyelinating Diseases / immunology
  • Demyelinating Diseases / physiopathology
  • Demyelinating Diseases / surgery*
  • Encephalitis / chemically induced
  • Encephalitis / diagnosis
  • Encephalitis / immunology
  • Encephalitis / physiopathology
  • Encephalitis / surgery*
  • Etanercept
  • Humans
  • Immunoglobulin G / adverse effects*
  • Immunohistochemistry
  • Immunosuppressive Agents / adverse effects*
  • Magnetic Resonance Imaging
  • Male
  • Receptors, Tumor Necrosis Factor
  • Recovery of Function
  • Spondylitis, Ankylosing / diagnosis
  • Spondylitis, Ankylosing / drug therapy*
  • Spondylitis, Ankylosing / immunology
  • Time Factors
  • Treatment Outcome
  • Tumor Necrosis Factor-alpha / antagonists & inhibitors
  • Tumor Necrosis Factor-alpha / immunology

Substances

  • Immunoglobulin G
  • Immunosuppressive Agents
  • Receptors, Tumor Necrosis Factor
  • Tumor Necrosis Factor-alpha
  • Etanercept