Treatment of acute decompensation of maple syrup urine disease in adult patients with a new parenteral amino-acid mixture

J Inherit Metab Dis. 2013 Nov;36(6):939-44. doi: 10.1007/s10545-012-9570-2. Epub 2012 Dec 19.

Abstract

Background: Acute decompensation of maple syrup urine disease (MSUD) is usually treated by enteral feeding with an amino-acid mixture without leucine (Leu), valine or isoleucine. However, its administration is ineffective in cases of gastric intolerance and some adult patients refuse enteral feeding via a nasogastric tube. We developed a new parenteral amino-acid mixture for patients with MSUD.

Methods: Seventeen decompensation episodes in four adult patients with MSUD treated with a parenteral amino-acid mixture (group P) were compared to 18 previous episodes in the same patients treated by enteral feeding (group E).

Results: The mean Leu concentration at presentation was similar in the groups P and E (1196.9 μmol/L and 1212.2 μmol/L, respectively). The mean decrease in the Leu concentration during the first 3 days of hospitalisation was significantly higher in group P than group E (p = 0.0026); there were no side effects. The mean duration of hospitalisation was similar (4 vs. 4.5 days, p = NS). No patient in group P deteriorated whereas one patient in group E required dialysis.

Conclusion: This new parenteral amino-acid mixture is safe and allows efficient Leu concentration decrease during acute MSUD decompensation episodes in adults. Its use avoids the need for nasogastric tube insertion.

Publication types

  • Clinical Trial

MeSH terms

  • Adult
  • Amino Acids / administration & dosage*
  • Female
  • Food, Formulated
  • Heart Failure / diet therapy*
  • Heart Failure / etiology
  • Hospitalization
  • Humans
  • Male
  • Maple Syrup Urine Disease / complications
  • Maple Syrup Urine Disease / diet therapy*
  • Parenteral Nutrition*
  • Patient Acceptance of Health Care
  • Young Adult

Substances

  • Amino Acids