[Analysis of CYP17A1 gene mutation in a child patient with 17 alpha-hydroxylase/17, 20-lyase deficiency]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2013 Aug;30(4):439-42. doi: 10.3760/cma.j.issn.1003-9406.2013.04.013.
[Article in Chinese]

Abstract

Objective: To analyze CYP17A1 gene mutations in a child patient with 17 alpha-hydroxylase/17, 20-lyase deficiency (17OHD), and to review characteristics of CYP17A1 gene mutations in Chinese patients with 17OHD.

Methods: Clinical data were collected. PCR and DNA sequencing were performed to detect mutations in the patient.

Results: The patient has presented classical features of 17OHD including hypertension, hypokalemia, decreased sex hormones and plasma cortisol, and elevated blood adrenocorticotrophic hormone. A compound heterozygous mutation c.987C>A and c.985del was detected in the CYP17A1 gene, which resulted in two premature stop codons at positions 328 and 417.

Conclusion: A compound mutation, c.987C>A and c.985del, has been identified in a patient with 17OHD. Among CYP17A1 gene mutations identified in Chinese patients, missence mutations have been most common, and exons 5 and 8 have been the mutation hotspots.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adrenal Hyperplasia, Congenital / enzymology*
  • Adrenal Hyperplasia, Congenital / genetics
  • Base Sequence
  • Female
  • Humans
  • Lyases / deficiency
  • Lyases / genetics*
  • Molecular Sequence Data
  • Mutation*
  • Steroid 17-alpha-Hydroxylase / genetics*

Substances

  • CYP17A1 protein, human
  • Steroid 17-alpha-Hydroxylase
  • Lyases