A cognitive chameleon: lessons from a novel MAPT mutation case

Neurocase. 2014;20(6):684-94. doi: 10.1080/13554794.2013.826697. Epub 2013 Sep 2.

Abstract

We report a case of frontotemporal dementia caused by a novel MAPT mutation (Q351R) with a remarkably long amnestic presentation mimicking familial Alzheimer's disease. Longitudinal clinical, neuropsychological and imaging data provide convergent evidence for predominantly bilateral anterior medial temporal lobe involvement consistent with previously established neuroanatomical signatures of MAPT mutations. This case supports the notion that the neural network affected in MAPT mutations is determined to a large extent by the underlying molecular pathology. We discuss the diagnostic significance of anomia in the context of atypical amnesia and the impact of impaired episodic and semantic memory systems on autobiographical memory.

Keywords: Autobiographical memory; Brain networks; Episodic memory; Familial Alzheimer’s disease; Frontotemporal dementia; MAPT mutations; Semantic memory.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alzheimer Disease / diagnosis
  • Amnesia / complications*
  • Anomia / complications
  • Brain / pathology
  • Disease Progression
  • Female
  • Frontotemporal Dementia / complications
  • Frontotemporal Dementia / diagnosis*
  • Frontotemporal Dementia / genetics*
  • Hippocampus / pathology
  • Humans
  • Middle Aged
  • Mutation*
  • tau Proteins / genetics*

Substances

  • MAPT protein, human
  • tau Proteins