Auditory outcome after cochlear implantation in patients with congenital nonsyndromic hearing loss: influence of the GJB2 status

Otol Neurotol. 2014 Sep;35(8):1361-5. doi: 10.1097/MAO.0000000000000348.

Abstract

Objective: To compare the audiologic outcome after cochlear implantation between 2 groups of patients with congenital nonsyndromic sensorineural hearing loss.

Study design: Retrospective cohort study.

Setting: Department of Otorhinolaryngology, University hospital (tertiary referral center).

Patients: From a bigger pool of implanted patients, 2 groups, each numbering 30 were enrolled. The patients from the first group were diagnosed with a Connexin 26 mutation (GJB2), whereas all of the patients from the second cohort were with a wild type genotype. Both groups were age matched, 1 to 7 years old at the age of implantation, with diagnosed congenital nonsyndromic sensorineural hearing loss.

Main outcome measures: Both groups were evaluated with the help evaluation of auditory responses to speech/EARS/test battery - LiP test (Listening Progress Profile), MTP tests 3,6,12 (Monosyllabic-Trochee-Polysyllabic Test), GASP test (Glendonald Auditory Screening Procedure), and others. Follow-up period was at least 36 months.

Results: Mean test scores were compared at the 1st, 6th, 12th, 24th, and 36th month. LiP outcome was significantly better (p < 0.05) for the GJB2-related cohort for the whole follow-up period except at the first month. MTP3, 6, and 12 tests displayed the same statistically significant outcome in favor of the first group. In the open-set test GASP, the difference was apparent: 1.22, 2.40, 5.59, and 7.40 mean scores at the 6th, 12th, 24, and 36th months for the first cohort versus 0.00, 0.07, 0.81, and 1.74 for the GJB2-unrelated patients.

Conclusion: The results from our study suggest that children with GJB2-related deafness show better auditory performance after cochlear implantation than age-matched children with GJB2-nonrelated sensorineural hearing loss.

MeSH terms

  • Child
  • Child, Preschool
  • Cochlear Implantation*
  • Cohort Studies
  • Connexin 26
  • Connexins / genetics*
  • Deafness / genetics
  • Deafness / surgery
  • Female
  • Genotype
  • Hearing Loss, Sensorineural / genetics
  • Hearing Loss, Sensorineural / surgery*
  • Humans
  • Infant
  • Male
  • Mutation
  • Retrospective Studies
  • Treatment Outcome

Substances

  • Connexins
  • GJB2 protein, human
  • Connexin 26

Supplementary concepts

  • Nonsyndromic Deafness
  • Nonsyndromic sensorineural hearing loss