Caspr2 antibody limbic encephalitis is associated with Hashimoto thyroiditis and thymoma

J Neurol Sci. 2014 Jun 15;341(1-2):36-40. doi: 10.1016/j.jns.2014.03.043. Epub 2014 Mar 29.

Abstract

Background: Contactin-associated protein 2 (Caspr2) antibody is a neuronal surface antibody (NSAb) capable of causing disorders involving central and peripheral nervous systems (PNS). Thymoma can be found in patients with Caspr2 antibodies and is most frequently associated with PNS symptoms. Myasthenia gravis can be found in these patients, but Hashimoto thyroiditis (HT) has not been reported.

Methods: A 76-year-old woman presented with sub-acute-onset changes in mental status. Further investigations revealed thymoma and HT. The presence of NSAb was tested by immunofluorescence on human embryonic kidney-293 cells. Treatment included corticosteroids, azathioprine, thyroxine, plasmapheresis, and thymectomy.

Results: Caspr2 antibody was positive in serum but absent in CSF. Brain magnetic resonance imaging (MRI) showed diffuse cortical atrophy, but did not change significantly after treatments. Brain positron emission tomography (PET) revealed diffuse hypometabolism over the cerebral cortex. The patient's mental status only partially improved.

Conclusions: In Caspr2 antibody-associated syndromes, thymoma can occur in patients presenting only with LE, and HT can be an accompanying disease. Brain MRI and PET may not show specific lesions in limbic area. Patients with Caspr2 antibodies and thymoma may not have good prognosis.

Keywords: Autoimmune encephalitis; Caspr2; Hashimoto thyroiditis; Neuronal surface antibodies; Thymoma; VGKC.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Antigens, Nuclear / immunology
  • Autoantibodies / blood*
  • Autoantibodies / cerebrospinal fluid*
  • Brain / diagnostic imaging
  • Brain / pathology
  • Case-Control Studies
  • Cell Line, Transformed
  • Female
  • Fluorodeoxyglucose F18
  • Follow-Up Studies
  • HEK293 Cells
  • Hashimoto Disease / complications*
  • Humans
  • Limbic Encephalitis / complications*
  • Limbic Encephalitis / diagnostic imaging
  • Limbic Encephalitis / drug therapy
  • Limbic Encephalitis / metabolism*
  • Magnetic Resonance Imaging
  • Membrane Proteins / immunology*
  • Nerve Tissue Proteins / immunology*
  • Positron-Emission Tomography
  • Thymoma / complications*
  • Thyroxine
  • Time Factors
  • Transfection

Substances

  • Antigens, Nuclear
  • Autoantibodies
  • CNTNAP2 protein, human
  • Membrane Proteins
  • Nerve Tissue Proteins
  • Fluorodeoxyglucose F18
  • Thyroxine