[Hereditary hemorrhagic telangiectasia. Report of a pediatric case]

Arch Pediatr. 2014 Jul;21(7):768-71. doi: 10.1016/j.arcped.2014.04.021. Epub 2014 Jun 13.
[Article in French]

Abstract

Hereditary hemorrhagic telangiectasia, or Rendu-Osler-Weber syndrome, is an autosomal dominant multiorgan disorder. This multisystemic vascular dysplasia is determined by a mutation of one of two main genes, endoglin (ENG) or HHT1, or ACVRL1 or HHT2. These mutations induce vascular disorders that cause recurrent epistaxis and eventually multiple telangiectasia and arteriovenous visceral malformations. We report the case of a 7-year-old girl who developed severe hypoxemia due to multiple pulmonary arteriovenous malformations.

Publication types

  • Case Reports

MeSH terms

  • Activin Receptors, Type II / genetics
  • Antigens, CD / genetics
  • Arteriovenous Malformations / complications
  • Arteriovenous Malformations / diagnostic imaging
  • Child
  • Endoglin
  • Female
  • Humans
  • Mutation
  • Radiography
  • Receptors, Cell Surface / genetics
  • Telangiectasia, Hereditary Hemorrhagic / complications
  • Telangiectasia, Hereditary Hemorrhagic / diagnosis*
  • Telangiectasia, Hereditary Hemorrhagic / genetics

Substances

  • Antigens, CD
  • ENG protein, human
  • Endoglin
  • Receptors, Cell Surface
  • ACVRL1 protein, human
  • Activin Receptors, Type II