The peculiar role of the A2V mutation in amyloid-β (Aβ) 1-42 molecular assembly

J Biol Chem. 2014 Aug 29;289(35):24143-52. doi: 10.1074/jbc.M114.576256. Epub 2014 Jul 18.

Abstract

We recently reported a novel Aβ precursor protein mutation (A673V), corresponding to position 2 of Aβ1-42 peptides (Aβ1-42A2V), that caused an early onset AD-type dementia in a homozygous individual. The heterozygous relatives were not affected as an indication of autosomal recessive inheritance of this mutation. We investigated the folding kinetics of native unfolded Aβ1-42A2V in comparison with the wild type sequence (Aβ1-42WT) and the equimolar solution of both peptides (Aβ1-42MIX) to characterize the oligomers that are produced in the early phases. We carried out the structural characterization of the three preparations using electron and atomic force microscopy, fluorescence emission, and x-ray diffraction and described the soluble oligomer formation kinetics by laser light scattering. The mutation promoted a peculiar pathway of oligomerization, forming a connected system similar to a polymer network with hydrophobic residues on the external surface. Aβ1-42MIX generated assemblies very similar to those produced by Aβ1-42WT, albeit with slower kinetics due to the difficulties of Aβ1-42WT and Aβ1-42A2V peptides in building up of stable intermolecular interaction.

Keywords: Alzheimer Disease; Amyloid; Amyloid Precursor Protein (APP); Amyloid-β (Aβ); Protein Aggregation.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Amyloid beta-Peptides / chemistry
  • Amyloid beta-Peptides / genetics*
  • Circular Dichroism
  • Humans
  • Kinetics
  • Microscopy, Atomic Force
  • Mutation*
  • Peptide Fragments / chemistry
  • Peptide Fragments / genetics*
  • Polymerization
  • Protein Folding
  • Scattering, Small Angle
  • Spectrometry, Fluorescence
  • X-Ray Diffraction

Substances

  • Amyloid beta-Peptides
  • Peptide Fragments
  • amyloid beta-protein (1-42)