Autoantibody Profiling in a Cohort of Pediatric and Adult Patients With Autoimmune Hepatitis

J Clin Lab Anal. 2016 Jan;30(1):41-6. doi: 10.1002/jcla.21813. Epub 2014 Sep 19.

Abstract

Background: Autoimmune hepatitis (AIH) is a rare condition characterized by the presence of autoantibodies distinctive of type 1 AIH (AIH-1) and type 2 AIH (AIH-2). The aim of this study was to evaluate the autoantibody profile in a cohort of pediatric and adult AIH patients, using both indirect immunofluorescence (IIF) and a new multiplexed line-blot assay.

Methods: Sera from 63 pediatric and 53 adult AIH patients were tested for antinuclear (ANA), antismooth muscle (SMA), anti-liver kidney microsome 1 (anti-LKM1), anti-liver cytosol 1 (anti-LC1) autoantibodies using IIF methods; for anti-LKM1, anti-LC1, and soluble liver antigen/liver-pancreas (anti-SLA/LP) autoantibodies using the line-blot; for anti-F-actin autoantibodies using IIF both on VSM47 cell-line and on rat intestinal epithelial cells.

Results: AIH-1 was the most common type of AIH in the adult cohort (73.6%), while AIH-2 was the most common AIH in the pediatric cohort (61.9%). Both in adult and pediatric AIH-2 anti-LKM1 were the prevalent autoantibodies. In pediatric AIH-2 anti-LC1 autoantibodies were more frequent than in adult AIH-2 (59 vs. 28.6%), and in 35.9% of cases they were present alone. In 17 patients anti-LC1 autoantibodies were detected only with the line-blot assay. The levels of anti-LKM1 and of anti-LC1 were not different between adult and pediatric AIH, and the overall agreement between the results obtained with the two IIF methods for F-actin detection was 98.8% (CI 95%: 94.4-99.7%).

Conclusions: The line-blot assay showed a higher sensitivity than IIF for anti-LC1 detection. Anti-LKM1 and anti-LC1 autoantibody levels are not different in adults and children. An almost perfect agreement between the two IIF methods for anti-F-actin detection has been observed.

Keywords: anti-F-actin; autoantibodies; autoimmune hepatitis; indirect immunofluorescence; multiplexed line-blot; reference intervals.

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Animals
  • Autoantibodies / blood*
  • Cell Line
  • Child
  • Child, Preschool
  • Cohort Studies
  • Demography
  • Epithelial Cells / metabolism
  • Female
  • Fluorescent Antibody Technique, Indirect
  • Hepatitis, Autoimmune / blood*
  • Hepatitis, Autoimmune / immunology*
  • Humans
  • Male
  • Middle Aged
  • Rats
  • Young Adult

Substances

  • Autoantibodies