[Infant rhabdoid tumors: a diagnostic emergency]

Arch Pediatr. 2014 Nov;21(11):1246-9. doi: 10.1016/j.arcped.2014.08.005. Epub 2014 Sep 26.
[Article in French]

Abstract

Rhabdoid tumors are a heterogeneous family of aggressive tumors affecting young children. Their grouping within a single entity is recent, following the discovery of a bi-allelic inactivation of the hSNF5/INI1 tumor suppressor gene in tumoral cells. This bi-allelic inactivation of the hSNF5/INI1 gene found at the constitutional level in up to one-third of cases has led to the identification of a predisposal syndrome to rhabdoid tumors. Herein we report extrarenal rhabdoid tumors observed in three infants between 3 and 6 months of age, underlining the misleading feature of the clinical presentation and the aggressiveness of the disease. Finally, we also report the genetic patient care management strategy.

Publication types

  • Case Reports

MeSH terms

  • Abdominal Neoplasms / diagnosis*
  • Abdominal Neoplasms / genetics
  • Abdominal Neoplasms / therapy
  • Alleles
  • Amniocentesis
  • Brain Neoplasms / diagnosis
  • Brain Neoplasms / genetics
  • Brain Neoplasms / therapy
  • Chromosomal Proteins, Non-Histone
  • Combined Modality Therapy
  • DNA Mutational Analysis
  • DNA-Binding Proteins
  • Emergencies*
  • Fatal Outcome
  • Female
  • Genes, Tumor Suppressor
  • Genetic Counseling
  • Humans
  • Infant
  • Liver Neoplasms / diagnosis*
  • Liver Neoplasms / genetics
  • Liver Neoplasms / therapy
  • Magnetic Resonance Imaging
  • Male
  • Pregnancy
  • Rhabdoid Tumor / diagnosis*
  • Rhabdoid Tumor / genetics
  • Rhabdoid Tumor / therapy
  • SMARCB1 Protein
  • Transcription Factors
  • Transcriptional Activation / genetics

Substances

  • Chromosomal Proteins, Non-Histone
  • DNA-Binding Proteins
  • SMARCB1 Protein
  • SMARCB1 protein, human
  • Transcription Factors