Argininosuccinate synthetase (ASS) deficiency in high-grade pulmonary neuroendocrine carcinoma: an opportunity for personalized targeted therapy

J Cancer Res Clin Oncol. 2015 Aug;141(8):1363-9. doi: 10.1007/s00432-014-1904-z. Epub 2014 Dec 30.

Abstract

Purpose: Cells deficient in argininosuccinate synthetase (ASS) must absorb the arginine they need for growth from circulating blood. Treatment with pegylated arginine deiminase (ADI-PEG 20) selectively eliminates arginine from the circulation and has shown some efficacy against ASS-deficient tumors including small cell lung cancer (SCLC). We sought to assess ASS expression in a cohort of high-grade pulmonary neuroendocrine carcinomas (PNEC) which include SCLC and large cell neuroendocrine carcinoma (LCNEC).

Methods: Sixty-nine PNEC (49 SCLC and 20 LCNEC) were retrieved from our pathology archives. Formalin-fixed paraffin-embedded sections of the 54 primary tumors, 15 metastases and appropriate positive and negative controls were immunostained using an ASS-specific monoclonal antibody. Positive staining in <30 % of the tumor was scored as weak; staining in ≥30 % of the tumor was scored as strong. The absence of staining in the tumor was recorded as ASS negative.

Results: 58 % of the PNEC including 61.2 % of the SCLC and 50 % of the LCNEC were ASS negative. These ASS-negative tumors included 63 % of the primary and 40 % of the metastatic lesions tested.

Conclusions: More than 50 % of the high-grade PNEC tested lack immunohistochemically detectable ASS, suggesting that they are auxotrophic for arginine and potential candidates for arginine deprivation therapy. PNEC comprise about 25 % of primary lung cancers and have a 5-year overall survival of only 5-10 %, underscoring the need for new and more effective therapies. Immunostaining for ASS has potential to improve the selection of patients with PNEC for arginine deprivation therapy with ADI-PEG 20.

MeSH terms

  • Aged
  • Aged, 80 and over
  • Argininosuccinate Synthase / deficiency*
  • Carcinoma, Neuroendocrine / enzymology
  • Carcinoma, Neuroendocrine / pathology
  • Carcinoma, Neuroendocrine / therapy*
  • Female
  • Humans
  • Hydrolases / therapeutic use*
  • Immunohistochemistry
  • Lung Neoplasms / enzymology
  • Lung Neoplasms / pathology
  • Lung Neoplasms / therapy*
  • Male
  • Middle Aged
  • Molecular Targeted Therapy / methods*
  • Neoplasm Grading
  • Patient Selection
  • Polyethylene Glycols / therapeutic use*
  • Precision Medicine / methods*
  • Small Cell Lung Carcinoma / epidemiology
  • Small Cell Lung Carcinoma / metabolism
  • Small Cell Lung Carcinoma / pathology
  • Small Cell Lung Carcinoma / therapy

Substances

  • Polyethylene Glycols
  • Hydrolases
  • ADI PEG20
  • Argininosuccinate Synthase