Automated external defibrillator rescues among children with diagnosed and treated long QT syndrome

Heart Rhythm. 2015 Apr;12(4):776-81. doi: 10.1016/j.hrthm.2015.01.002. Epub 2015 Jan 7.

Abstract

Background: Long QT syndrome (LQTS) is a potentially lethal yet highly treatable cardiac channelopathy. A comprehensive LQTS-directed treatment program often includes an automated external defibrillator (AED).

Objective: The purpose of this study was to determine the incidence of AED rescues among children evaluated, risk-stratified, and treated in an LQTS specialty center.

Methods: We performed a retrospective review of the electronic medical records to identify 1665 patients evaluated in our Genetic Heart Rhythm Clinic (1999-2013). Subset analysis was performed on 291 children managed without an implantable cardioverter-defibrillator (ICD).

Results: The average age at diagnosis was 8.3 ± 5.7 years with an average. QTc of 463 ± 40 ms (17% ≥500 ms). The represented LQTS genotypes included type 1 (LQT1) in 52%, type 2 (LQT2) in 35%, and type 3 (LQT3) in 7%. During follow-up, 3 of 291 children (1%) had a cardiac arrest with an appropriate AED rescue (2/51 symptomatic, 1/240 asymptomatic). The first AED rescue occurred during exercise in a symptomatic 3-year-old boy with compound LQT1 treated with beta-blocker and videoscopic left cardiac sympathetic denervation (LCSD). The second AED rescue occurred in a remotely symptomatic 14-year-old boy with high-risk LQT2 (QTc >550 ms) on a beta-blocker who previously declined a prophylactic ICD. The third AED rescue involved an asymptomatic 17-year-old girl with LQT3 on mexiletine who collapsed in school.

Conclusion: An AED should seldom be necessary in an appropriately treated child with LQTS. Nevertheless, despite only 3 AED rescues in more than 1700 patient-years, an AED can be a lifesaving and cost-effective part of an LQTS patient's comprehensive sudden death prevention program.

Keywords: Automated external defibrillator; Long QT syndrome; Out-of-hospital cardiac arrest; Sudden cardiac death; Ventricular fibrillation.

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Death, Sudden, Cardiac / prevention & control
  • Defibrillators* / statistics & numerical data
  • Electric Countershock* / instrumentation
  • Electric Countershock* / methods
  • Electric Countershock* / statistics & numerical data
  • Female
  • Humans
  • Incidence
  • Long QT Syndrome / diagnosis
  • Long QT Syndrome / etiology
  • Long QT Syndrome / mortality
  • Long QT Syndrome / therapy*
  • Male
  • Medical Records
  • Out-of-Hospital Cardiac Arrest / etiology
  • Out-of-Hospital Cardiac Arrest / therapy*
  • Retrospective Studies
  • United States / epidemiology