Genome-wide association study of recalcitrant atopic dermatitis in Korean children

J Allergy Clin Immunol. 2015 Sep;136(3):678-684.e4. doi: 10.1016/j.jaci.2015.03.030. Epub 2015 Apr 30.

Abstract

Background: Atopic dermatitis (AD) is a heterogeneous chronic inflammatory skin disease. Most AD during infancy resolves during childhood, but moderate-to-severe AD with allergic sensitization is more likely to persist into adulthood and more often occurs with other allergic diseases.

Objective: We sought to find susceptibility loci by performing the first genome-wide association study (GWAS) of AD in Korean children with recalcitrant AD, which was defined as moderate-to-severe AD with allergic sensitization.

Methods: Our study included 246 children with recalcitrant AD and 551 adult control subjects with a negative history of both allergic disease and allergic sensitization. DNA from these subjects was genotyped; sets of common single nucleotide polymorphisms (SNPs) were imputed and used in the GWAS after quality control checks.

Results: SNPs at a region on 13q21.31 were associated with recalcitrant AD at a genome-wide threshold of significance (P < 2.0 × 10(-8)). These associated SNPs are more than 1 Mb from the closest gene, protocadherin (PCDH)9. SNPs at 4 additional loci had P values of less than 1 × 10(-6), including SNPs at or near the neuroblastoma amplified sequence (NBAS; 2p24.3), thymus-expressed molecule involved in selection (THEMIS; 6q22.33), GATA3 (10p14), and S-phase cyclin A-associated protein in the ER (SCAPER; 15q24.3) genes. Further analysis of total serum IgE levels suggested 13q21.31 might be primarily an IgE locus, and analyses of published data demonstrated that SNPs at the 15q24.3 region are expression quantitative trait loci for 2 nearby genes, ISL2 and proline-serine-threonine phosphatase interacting protein 1 (PSTPIP1), in immune cells.

Conclusion: Our GWAS of recalcitrant AD identified new susceptibility regions containing genes involved in epithelial cell function and immune dysregulation, 2 key features of AD, and potentially extend our understanding of their role in pathogenesis.

Keywords: Genome-wide association study; IgE; allergic sensitization; atopic dermatitis; children; severity.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adaptor Proteins, Signal Transducing / genetics
  • Adaptor Proteins, Signal Transducing / immunology
  • Adolescent
  • Adult
  • Asian People
  • Cadherins / genetics
  • Cadherins / immunology
  • Carrier Proteins / genetics
  • Carrier Proteins / immunology
  • Case-Control Studies
  • Child
  • Child, Preschool
  • Chromosomes, Human, Pair 13
  • Chromosomes, Human, Pair 15
  • Cytoskeletal Proteins / genetics
  • Cytoskeletal Proteins / immunology
  • Dermatitis, Atopic / ethnology
  • Dermatitis, Atopic / genetics*
  • Dermatitis, Atopic / immunology
  • Dermatitis, Atopic / pathology
  • Female
  • GATA3 Transcription Factor / genetics
  • GATA3 Transcription Factor / immunology
  • Genetic Predisposition to Disease*
  • Genome-Wide Association Study
  • Humans
  • Immunoglobulin E / genetics*
  • Immunoglobulin E / immunology
  • Intracellular Signaling Peptides and Proteins / genetics
  • Intracellular Signaling Peptides and Proteins / immunology
  • LIM-Homeodomain Proteins / genetics
  • LIM-Homeodomain Proteins / immunology
  • Male
  • Neoplasm Proteins / genetics
  • Neoplasm Proteins / immunology
  • Nerve Tissue Proteins / genetics
  • Nerve Tissue Proteins / immunology
  • Polymorphism, Single Nucleotide
  • Protocadherins
  • Quantitative Trait Loci*
  • Severity of Illness Index
  • Transcription Factors / genetics
  • Transcription Factors / immunology

Substances

  • Adaptor Proteins, Signal Transducing
  • Cadherins
  • Carrier Proteins
  • Cytoskeletal Proteins
  • GATA3 Transcription Factor
  • GATA3 protein, human
  • ISL2 protein, human
  • Intracellular Signaling Peptides and Proteins
  • LIM-Homeodomain Proteins
  • NBAS protein, human
  • Neoplasm Proteins
  • Nerve Tissue Proteins
  • PCDH9 protein, human
  • PSTPIP1 protein, human
  • Protocadherins
  • SCAPER protein, human
  • Transcription Factors
  • thymocyte-expressed molecule involved in selection, human
  • Immunoglobulin E