Atypical teratoid rhabdoid tumor: long-term survival after chemoradiotherapy

Childs Nerv Syst. 2015 Aug;31(8):1393-9. doi: 10.1007/s00381-015-2723-5. Epub 2015 May 5.

Abstract

Purpose: Atypical teratoid rhabdoid tumors (ATRTs) arise from the central nervous system largely in the pediatric population. They portend a very poor prognosis with few long-term survivors. We describe a series of five cases at our institution.

Methods: We conducted a retrospective chart review and clinical follow-up.

Results: Three patients underwent chemoradiation after surgical resection; the two patients whose caretakers declined this therapy passed away soon after diagnosis. Chemoradiation included intravenous and intrathecal chemotherapy as well as intensity-modulated radiotherapy after resection. Of the patients receiving chemoradiation, two patients had infratentorial tumors, two had gross residual tumor after resection, and two were under the age of 3 years. The three patients receiving trimodality therapy remain clinically and symptomatically disease-free with follow-up times of 44, 46, and 55 months. Two of the patients have mild neuropsychiatric sequelae after therapy.

Conclusions: Long-term, high-volume trials of ATRT are currently not published. We offer experience in successful long-term survival of this tumor treated with chemoradiotherapy.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Central Nervous System Neoplasms / drug therapy*
  • Chemoradiotherapy / methods*
  • Child
  • Child, Preschool
  • Disease-Free Survival
  • Female
  • Humans
  • Magnetic Resonance Imaging
  • Male
  • Retrospective Studies
  • Rhabdoid Tumor / drug therapy*
  • Survivors*
  • Teratoma / drug therapy*