Senior-Loken syndrome secondary to NPHP5/IQCB1 mutation in an Iranian family

NDT Plus. 2011 Dec;4(6):421-3. doi: 10.1093/ndtplus/sfr096. Epub 2011 Aug 18.

Abstract

Senior-Loken syndrome (SLS) is a rare autosomal recessive disease characterized by nephronophthisis and early-onset retinal degeneration. We used a large Iranian family with SLS to establish a molecular genetic diagnosis. Following clinical evaluation, we undertook homozygosity mapping in two affected family members and mutational analysis in known SLS genes coinciding with regions of homozygosity. In a region of homozygosity coinciding with a known SLS locus on chromosome 3q21.1, we found a homozygous non-sense mutation R332X in NPHP5/IQCB1. This is the first report of a molecular genetic diagnosis in an Iranian kindred with SLS.

Keywords: Iran; Senior-Lokensyndrome; homozygosity mapping; mutation; nephronophthisis.

Publication types

  • Case Reports