Intraoperative Electron-Beam Radiation Therapy for Pediatric Ewing Sarcomas and Rhabdomyosarcomas: Long-Term Outcomes

Int J Radiat Oncol Biol Phys. 2015 Aug 1;92(5):1069-1076. doi: 10.1016/j.ijrobp.2015.04.048. Epub 2015 May 2.

Abstract

Purpose: To assess long-term outcomes and toxicity of intraoperative electron-beam radiation therapy (IOERT) in the management of pediatric patients with Ewing sarcomas (EWS) and rhabdomyosarcomas (RMS).

Methods and materials: Seventy-one sarcoma (EWS n=37, 52%; RMS n=34, 48%) patients underwent IOERT for primary (n=46, 65%) or locally recurrent sarcomas (n=25, 35%) from May 1983 to November 2012. Local control (LC), overall survival (OS), and disease-free survival were estimated using Kaplan-Meier methods. For survival outcomes, potential associations were assessed in univariate and multivariate analyses using the Cox proportional hazards model.

Results: After a median follow-up of 72 months (range, 4-310 months), 10-year LC, disease-free survival, and OS was 74%, 57%, and 68%, respectively. In multivariate analysis after adjustment for other covariates, disease status (P=.04 and P=.05) and R1 margin status (P<.01 and P=.04) remained significantly associated with LC and OS. Nine patients (13%) reported severe chronic toxicity events (all grade 3).

Conclusions: A multimodal IOERT-containing approach is a well-tolerated component of treatment for pediatric EWS and RMS patients, allowing reduction or substitution of external beam radiation exposure while maintaining high local control rates.

Publication types

  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Analysis of Variance
  • Antineoplastic Combined Chemotherapy Protocols / therapeutic use
  • Bone Neoplasms / drug therapy
  • Bone Neoplasms / mortality
  • Bone Neoplasms / radiotherapy*
  • Bone Neoplasms / surgery
  • Child
  • Child, Preschool
  • Combined Modality Therapy / adverse effects
  • Combined Modality Therapy / methods
  • Combined Modality Therapy / mortality
  • Disease-Free Survival
  • Electrons / therapeutic use*
  • Female
  • Follow-Up Studies
  • Humans
  • Induction Chemotherapy / methods
  • Intraoperative Care
  • Male
  • Neoplasm Recurrence, Local / mortality
  • Neoplasm Recurrence, Local / radiotherapy*
  • Neoplasm Recurrence, Local / surgery
  • Radiotherapy Dosage
  • Rhabdomyosarcoma / mortality
  • Rhabdomyosarcoma / radiotherapy*
  • Rhabdomyosarcoma / surgery
  • Sarcoma, Ewing / drug therapy
  • Sarcoma, Ewing / mortality
  • Sarcoma, Ewing / radiotherapy*
  • Sarcoma, Ewing / surgery
  • Time Factors
  • Young Adult