Acute bulbar palsy as a variant of Guillain-Barré syndrome

Neurology. 2016 Feb 23;86(8):742-7. doi: 10.1212/WNL.0000000000002256. Epub 2015 Dec 30.

Abstract

Objective: To categorize a syndrome manifesting as prominent acute bulbar palsy (ABP) without limb motor weakness as a variant form of Guillain-Barré syndrome (GBS) and differentiate it from Miller Fisher syndrome (MFS) and pharyngeal-cervical-brachial (PCB) variants.

Methods: We analyzed cases of ABP without limb motor weakness based on a dataset containing clinical information and the results of antiganglioside antibodies assays for acute immune-mediated neuropathies.

Results: Eleven cases with an age at onset ranging from 18 to 65 years (mean 33.8 years) were identified as ABP-plus syndrome. All of the enrolled cases manifested with ABP as the predominant symptom, and with no limb weakness. The following features accompanied ABP in order of decreasing frequency: ophthalmoplegia (n = 9, 82%), ataxia (n = 9, 82%), and facial palsy (n = 6, 55%). An enzyme-linked immunosorbent assay study disclosed that immunoglobulin G (IgG) anti-GT1a antibodies were the most frequent (n = 11), followed by IgG anti-GQ1b antibodies (n = 6).

Conclusions: We propose that ABP-plus syndrome without neck or limb weakness is a variant of GBS that is distinct from the MFS and PCB variants. The presence of IgG anti-GT1a antibodies can explain the relationships between the distinct clinical characteristics and the underlying pathomechanisms.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Autoantibodies / blood
  • Bulbar Palsy, Progressive / blood*
  • Bulbar Palsy, Progressive / classification
  • Bulbar Palsy, Progressive / diagnosis*
  • Databases, Factual
  • Female
  • Guillain-Barre Syndrome / blood*
  • Guillain-Barre Syndrome / classification
  • Guillain-Barre Syndrome / diagnosis*
  • Humans
  • Immunoglobulin G / blood
  • Male
  • Middle Aged
  • Young Adult

Substances

  • Autoantibodies
  • Immunoglobulin G