Chylomicron retention disease: A rare cause of chronic diarrhea

Arch Pediatr. 2016 Jul;23(7):735-7. doi: 10.1016/j.arcped.2016.04.010. Epub 2016 Jun 3.

Abstract

Chylomicron retention disease (CRD) is a rare autosomal recessive hereditary hypocholesterolemic disorder. The disease most frequently presents in infants and is characterized by a lipid malabsorption syndrome with steatorrhea, chronic diarrhea, and growth retardation. The disease is characterized by normal fasting serum triglyceride levels combined with the absence of apolipoprotein (apo) B48 and chylomicrons after a fat load. In this report, we describe the clinical, laboratory, and histological data as well as the molecular DNA analysis of a 12-month-old girl from Tunisia with CRD. The patient was treated with a low-fat diet and fat-soluble vitamin supplementation resulting in significant improvement.

Publication types

  • Case Reports

MeSH terms

  • Chronic Disease
  • Diarrhea / etiology*
  • Failure to Thrive / etiology
  • Female
  • Humans
  • Hypobetalipoproteinemias / complications*
  • Hypobetalipoproteinemias / diagnosis
  • Hypobetalipoproteinemias / genetics
  • Infant
  • Malabsorption Syndromes / complications*
  • Malabsorption Syndromes / diagnosis
  • Malabsorption Syndromes / genetics
  • Monomeric GTP-Binding Proteins / genetics
  • Mutation

Substances

  • SAR1B protein, human
  • Monomeric GTP-Binding Proteins

Supplementary concepts

  • Chylomicron retention disease