Multimodal Imaging in Wagner Syndrome

Ophthalmic Surg Lasers Imaging Retina. 2016 Jun 1;47(6):574-9. doi: 10.3928/23258160-20160601-10.

Abstract

Wagner syndrome is a rare vitreoretinopathy described in a limited number of families. Here the authors describe four cases of suspected Wagner syndrome. All four cases had depressed rod and cone function on electroretinography, outer retinal disruption on spectral-domain optical coherence tomography, and constricted central visual fields with smaller isopter testing. Fundus autofluorescence performed in one patient highlighted a perivascular pattern to chorioretinal atrophy. Two patients had a history of uveitis with active cystoid macular edema. The diagnosis of Wagner syndrome was supported in three cases with genetic testing for VCAN mutations, whereas the other case harbored a variation of unknown significance in VCAN that may have been nonpathogenic. [Ophthalmic Surg Lasers Imaging Retina. 2016;47:574-579.].

Publication types

  • Case Reports
  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adult
  • Child
  • Electroretinography
  • Female
  • Fluorescein Angiography / methods
  • Fundus Oculi
  • Humans
  • Male
  • Middle Aged
  • Multimodal Imaging / methods*
  • Retina / diagnostic imaging*
  • Retina / physiopathology
  • Retinal Degeneration / diagnosis*
  • Tomography, Optical Coherence / methods
  • Versicans / deficiency*
  • Visual Acuity*

Substances

  • Versicans

Supplementary concepts

  • Hyaloideoretinal degeneration of Wagner