Significant Association of the RNF213 p.R4810K Polymorphism with Quasi-Moyamoya Disease

J Stroke Cerebrovasc Dis. 2016 Nov;25(11):2632-2636. doi: 10.1016/j.jstrokecerebrovasdis.2016.07.004. Epub 2016 Jul 28.

Abstract

Background: Quasi-moyamoya disease is an angiographical moyamoya disease equivalent accompanied by known underlying diseases. Mysterin/RNF213 is a major susceptibility gene for moyamoya disease, of which the p.R4810K variant is a founder polymorphism. The genetics of quasi-moyamoya disease is poorly understood, therefore, this study investigated a potential association between the p.R4810K polymorphism and quasi-moyamoya disease.

Methods: Genotyping of the p.R4810K variant was performed on 18 quasi-moyamoya disease cases and 91 controls, who visited Kyoto University Hospital or Kobe City Medical Center, Japan, between 2006 and 2015.

Results: The p.R4810K variant was found in 12 of 18 quasi-moyamoya disease patients. The frequency of p.R4810K carriers was significantly higher in quasi-moyamoya disease cases than in controls (66.7% versus 2.2%, odds ratio 89.0, 95% confidence interval: 19.2-669.4).

Conclusions: Our data showed that the RNF213 p.R4810K polymorphism was significantly associated with quasi-moyamoya disease.

Keywords: Moyamoya disease; RNF213; epidemiology; genetics.

Publication types

  • Multicenter Study

MeSH terms

  • Adenosine Triphosphatases / genetics*
  • Adolescent
  • Adult
  • Aged
  • Case-Control Studies
  • Cerebral Angiography / methods
  • Child
  • Child, Preschool
  • Female
  • Genetic Association Studies
  • Genetic Predisposition to Disease
  • Humans
  • Japan
  • Logistic Models
  • Magnetic Resonance Angiography
  • Male
  • Middle Aged
  • Moyamoya Disease / diagnostic imaging
  • Moyamoya Disease / genetics*
  • Odds Ratio
  • Phenotype
  • Polymorphism, Genetic*
  • Risk Factors
  • Ubiquitin-Protein Ligases / genetics*
  • Young Adult

Substances

  • RNF213 protein, human
  • Ubiquitin-Protein Ligases
  • Adenosine Triphosphatases