[Analysis of diagnosis and treatment of Alport syndrome]

Zhonghua Er Ke Za Zhi. 2016 Sep;54(9):669-73. doi: 10.3760/cma.j.issn.0578-1310.2016.09.008.
[Article in Chinese]

Abstract

Objective: To investigate the clinical characteristics and the status of diagnosis and treatment of patients with Alport syndrome in China.

Method: Patients with affirmative diagnosis of Alport syndrome from Department of Pedatrics, Peking University First Hospital in the past 20 years (1995-2015) were analyzed retrospectively. The clinical data including initial symptoms, visit reasons, age at onset of disease, family history, hereditary mode, methods of diagnosis, misdiagnosis and mistreatment were collected.

Result: A total of 398 patients with Alport syndrome were included in this study, 48.2% of patients had the onset of symptoms before age of 3 years. The rate of onset of symptoms and diagnosis before age of 17 years were 95.7%. The initial symptoms included gross hematuria (37.2%), microscopic hematuria and proteinuria (25.1%), microscopic hematuria (14.8%), edema of eyelid and lower limbs (10.3%), increased foam in urine (4.3%), etc.; 39.5% of patients had no symptoms of urinary tract. Only 14.0% of the patients were diagnosed as Alport syndrome for the first time, and 86.0% of the patients were misdiagnosed. Hormones and immunosuppressive agents were used in 19.0% of patients diagnosed as Alport syndrome, and in 43.0% of patients there was misdiagnosis. Skin biopsy and immunofluorescence of type Ⅳ collagen ɑ5 chain in epithelial basement membrane had a detection rate of 77.8%. Electron microscopy of glomerular basement membrane had a detection rate of 92.6%, and genetic testing 96.6%. The time interval of diagnosis was 18.2 months and was gradually shortened in recent years.

Conclusion: Alport syndrome developed at a very young age. Hematuria was the most frequent initial symptom. There was a high rate of misdiagnosis and mistreatment for Alport syndrome. Genetic testing for Alport syndrome had advantages of high detection rate, genetic consultation and prenatal diagnosis.

MeSH terms

  • Adolescent
  • Basement Membrane
  • Child
  • Child, Preschool
  • China
  • Collagen Type IV
  • Diagnostic Errors
  • Edema
  • Female
  • Fluorescent Antibody Technique
  • Genetic Testing
  • Hematuria
  • Humans
  • Immunosuppressive Agents
  • Male
  • Microscopy, Electron
  • Nephritis, Hereditary / diagnostic imaging*
  • Nephritis, Hereditary / therapy*
  • Pregnancy
  • Prenatal Diagnosis
  • Proteinuria
  • Retrospective Studies
  • Skin

Substances

  • Collagen Type IV
  • Immunosuppressive Agents