NKX2-5 molecular screening and assessment of variant rate and risk factors of secundum atrial septal defect in a Moroccan population

Anatol J Cardiol. 2017 Mar;17(3):217-223. doi: 10.14744/AnatolJCardiol.2016.7222. Epub 2016 Oct 12.

Abstract

Objective: Secundum atrial septal defect (ASDII) has multifactorial etiology that is combination of environmental (e.g., mother's exposure to toxicity, ethnicity) and genetic causes. Aim of the present study was to screen a Moroccan population with ASDII for NKX2-5 variants and to assess risk factors that may contribute to emergence of the disorder.

Methods: Thirty-two non-syndromic ASDII patients were screened for NKX2-5 variants using direct sequencing of polymerase chain reactionamplified coding regions. Risk factor rates were compared to general population and assessed using Fisher's exact and chi-square tests. In this retrospective study, criteria of exclusion were suggestive or confirmed syndrome association.

Results: Three heterozygous variants were detected in 4 patients. NKX2-5 variant rate in present cohort is estimated to be about 9.4%. Two prominent risk factors in the Moroccan population were highlighted: consanguinity, rate of which was significantly high at 30.8%, and previous maternal miscarriage or sibling sudden death, observed in 34.6% of cohort.

Conclusion: Impact of identified variants was discussed and possible disease-predisposing effect is suggested. Findings indicate that ASD may be favored by consanguineous marriage and that NKX2-5 variant rate in ASD patients may be affected by ethnicity. High level of maternal miscarriage and sibling sudden death suggests potential non-sporadic nature as result of putative genetic defect.

MeSH terms

  • Adolescent
  • Adult
  • Child
  • Child, Preschool
  • Cohort Studies
  • Female
  • Genetic Markers / genetics
  • Heart Septal Defects, Atrial / blood
  • Heart Septal Defects, Atrial / epidemiology*
  • Heart Septal Defects, Atrial / genetics*
  • Homeobox Protein Nkx-2.5 / blood
  • Homeobox Protein Nkx-2.5 / genetics*
  • Humans
  • Infant
  • Male
  • Morocco / epidemiology
  • Retrospective Studies
  • Risk Factors
  • White People / genetics
  • Young Adult

Substances

  • Genetic Markers
  • Homeobox Protein Nkx-2.5
  • NKX2-5 protein, human