Chronic Granulomatous Disease Due to Neutrophil Cytosolic Factor (NCF2) Gene Mutations in Three Unrelated Families

J Clin Immunol. 2017 Feb;37(2):109-112. doi: 10.1007/s10875-016-0366-2. Epub 2016 Dec 29.

Abstract

Chronic granulomatous disease (CGD) is an inheritable and genetically heterogeneous disease resulting from mutations in different subcomponents of the NADPH oxidase system. Mutations in the NCF2 gene account for <5% of all cases of CGD. We analyzed the clinical and laboratory findings of CGD with mutations in the NCF2 gene from amongst our cohort of CGD patients. A homozygous mutation (c.835_836delAC, p.T279fsX294), a deletion in NCF2 gene was found in two cases. In the third case, two heterozygous mutations were detected, IVS13-2A>T on one allele and c.1099C>T (p.) on the other allele. The mother of this child was a carrier for the IVS13-2A>T mutation. All three cases had colitis, and it was the initial symptom in two patients. One of the patients also developed a lung abscess due to Nocardia cyriacigeorgica.

Keywords: Chronic granulomatous disease; autosomal recessive; colitis; dihydrorhodamine 123 assay; mutation; neutrophil cytosolic fraction 2 gene; p67phox protein.

Publication types

  • Case Reports
  • Letter

MeSH terms

  • Child, Preschool
  • DNA Mutational Analysis
  • Family
  • Genes, Recessive
  • Genetic Association Studies*
  • Genetic Predisposition to Disease*
  • Genotype
  • Granulomatous Disease, Chronic / diagnosis*
  • Granulomatous Disease, Chronic / genetics*
  • Humans
  • Infant
  • Male
  • Mutation*
  • NADPH Oxidases / genetics*
  • Neutrophils / immunology
  • Neutrophils / metabolism
  • Radiography, Thoracic
  • Tomography, X-Ray Computed

Substances

  • NADPH Oxidases
  • NCF2 protein, human