Anti-HMGCR Autoantibodies in Juvenile Idiopathic Inflammatory Myopathies Identify a Rare but Clinically Important Subset of Patients

J Rheumatol. 2017 Apr;44(4):488-492. doi: 10.3899/jrheum.160871. Epub 2017 Feb 15.

Abstract

Objective: We aimed to establish the prevalence and clinical associations of anti-HMG-CoA-reductase (anti-HMGCR) in a large UK cohort with juvenile myositis.

Methods: There were 381 patients investigated for anti-HMGCR using ELISA.

Results: Anti-HMGCR autoantibodies were detected in 4 patients (1%). These children had no or minimal rash and significant muscle disease. Muscle biopsies were considered distinctive, with widespread variation in fiber size, necrotic fibers, and chronic inflammatory cell infiltrates; all had prolonged elevation of creatine kinase and all ultimately received biologic therapies.

Conclusion: Anti-HMGCR in UK children with myositis are associated with severe disease that is poorly responsive to standard treatment.

Keywords: AUTOANTIBODIES; PEDIATRIC DERMATOMYOSITIS/POLYMYOSITIS; PEDIATRIC RHEUMATIC DISEASES; PROGNOSIS.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Anti-Inflammatory Agents / therapeutic use
  • Autoantibodies / blood
  • Autoantibodies / immunology*
  • Child
  • Child, Preschool
  • Enzyme-Linked Immunosorbent Assay
  • Female
  • Humans
  • Hydroxymethylglutaryl CoA Reductases / immunology*
  • Male
  • Myositis / blood
  • Myositis / diagnosis*
  • Myositis / drug therapy
  • Myositis / immunology
  • Treatment Outcome

Substances

  • Anti-Inflammatory Agents
  • Autoantibodies
  • HMGCR protein, human
  • Hydroxymethylglutaryl CoA Reductases