Phenotypic Screening Identifies Modulators of Amyloid Precursor Protein Processing in Human Stem Cell Models of Alzheimer's Disease

Stem Cell Reports. 2017 Apr 11;8(4):870-882. doi: 10.1016/j.stemcr.2017.02.006. Epub 2017 Mar 9.

Abstract

Human stem cell models have the potential to provide platforms for phenotypic screens to identify candidate treatments and cellular pathways involved in the pathogenesis of neurodegenerative disorders. Amyloid precursor protein (APP) processing and the accumulation of APP-derived amyloid β (Aβ) peptides are key processes in Alzheimer's disease (AD). We designed a phenotypic small-molecule screen to identify modulators of APP processing in trisomy 21/Down syndrome neurons, a complex genetic model of AD. We identified the avermectins, commonly used as anthelmintics, as compounds that increase the relative production of short Aβ peptides at the expense of longer, potentially more toxic peptides. Further studies demonstrated that this effect is not due to an interaction with the core γ-secretase responsible for Aβ production. This study demonstrates the feasibility of phenotypic drug screening in human stem cell models of Alzheimer-type dementia, and points to possibilities for indirectly modulating APP processing, independently of γ-secretase modulation.

Keywords: Alzheimer's disease; Down syndrome; amyloid beta; dementia; human neurons; iPSCs; ivermectin; neural stem cells; phenotypic screening; selamectin.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Alzheimer Disease / drug therapy*
  • Alzheimer Disease / metabolism
  • Alzheimer Disease / pathology
  • Amyloid Precursor Protein Secretases / metabolism
  • Amyloid beta-Protein Precursor / metabolism*
  • Anthelmintics / chemistry
  • Anthelmintics / pharmacology*
  • Cells, Cultured
  • Down Syndrome / metabolism
  • Down Syndrome / pathology
  • Drug Discovery / methods*
  • Humans
  • Induced Pluripotent Stem Cells / metabolism
  • Induced Pluripotent Stem Cells / pathology
  • Ivermectin / analogs & derivatives*
  • Ivermectin / chemistry
  • Ivermectin / pharmacology
  • Neurogenesis
  • Neurons / drug effects*
  • Neurons / metabolism
  • Neurons / pathology
  • Phenotype

Substances

  • Amyloid beta-Protein Precursor
  • Anthelmintics
  • Ivermectin
  • avermectin
  • Amyloid Precursor Protein Secretases