The silent mutation MLH1 c.543C>T resulting in aberrant splicing can cause Lynch syndrome: a case report

Jpn J Clin Oncol. 2017 Jun 1;47(6):576-580. doi: 10.1093/jjco/hyx023.

Abstract

The proband was a 67-year-old man with transverse and sigmoid colon cancer. Microsatellite instability analysis revealed a high frequency of microsatellite instability, and immunohistochemical staining showed the absence of both MLH1 and PMS2 proteins in the sigmoid colon cancer tissue specimens from the patient. DNA sequencing revealed a nucleotide substitution c.543C>T in MLH1, but this variant did not substitute an amino acid. The MLH1 c.543C>T variant was located 3 bases upstream from the end of exon 6 and created a new splice donor site 4 bases upstream from the end of exon 6. Consequently, the last 4 bases of exon 6 were deleted and frameshift occurred. Thus, the MLH1 c.543C>T silent mutation is considered 'pathogenic'.

Keywords: Lynch syndrome; colon cancer; silent mutation.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Alternative Splicing / genetics
  • Base Sequence
  • Colorectal Neoplasms, Hereditary Nonpolyposis / genetics*
  • Colorectal Neoplasms, Hereditary Nonpolyposis / pathology
  • DNA Mutational Analysis
  • Female
  • Humans
  • Immunohistochemistry
  • Male
  • Middle Aged
  • MutL Protein Homolog 1 / genetics*
  • Pedigree
  • Sequence Analysis, RNA
  • Silent Mutation / genetics*

Substances

  • MLH1 protein, human
  • MutL Protein Homolog 1