Selective inhibition of nuclear export with selinexor in patients with non-Hodgkin lymphoma

Blood. 2017 Jun 15;129(24):3175-3183. doi: 10.1182/blood-2016-11-750174. Epub 2017 May 3.

Abstract

Patients with relapsed or refractory (R/R) non-Hodgkin lymphoma (NHL) have a poor prognosis and limited treatment options. We evaluated selinexor, an orally bioavailable, first-in-class inhibitor of the nuclear export protein XPO1, in this phase 1 trial to assess safety and determine a recommended phase 2 dose (RP2D). Seventy-nine patients with various NHL histologies, including diffuse large B-cell lymphoma, Richter's transformation, mantle cell lymphoma, follicular lymphoma, and chronic lymphocytic leukemia, were enrolled. In the dose-escalation phase, patients received 3 to 80 mg/m2 of selinexor in 3- or 4-week cycles and were assessed for toxicities, pharmacokinetics, and antitumor activity. In the dose-expansion phase, patients were treated with selinexor at 35 or 60 mg/m2 The most common grade 3 to 4 drug-related adverse events were thrombocytopenia (47%), neutropenia (32%), anemia (27%), leukopenia (16%), fatigue (11%), and hyponatremia (10%). Tumor biopsies showed decreases in cell-signaling pathways (Bcl-2, Bcl-6, c-Myc), reduced proliferation (Ki67), nuclear localization of XPO1 cargos (p53, PTEN), and increased apoptosis after treatment. Twenty-two (31%) of the 70 evaluable patients had an objective responses, including 4 complete responses and 18 partial responses, which were observed across a spectrum of NHL subtypes. A dose of 35 mg/m2 (60 mg) was identified as the RP2D. These findings suggest that inhibition of XPO1 with oral selinexor at 35 mg/m2 is a safe therapy with encouraging and durable anticancer activity in patients with R/R NHL. The trial was registered at www.clinicaltrials.gov as #NCT01607892.

Publication types

  • Clinical Trial, Phase I
  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Active Transport, Cell Nucleus / drug effects
  • Adult
  • Aged
  • Aged, 80 and over
  • Anemia / chemically induced
  • Anemia / metabolism
  • Anemia / pathology
  • Apoptosis / drug effects
  • Cell Nucleus / metabolism*
  • Cell Nucleus / pathology
  • Dose-Response Relationship, Drug
  • Female
  • Humans
  • Hydrazines / administration & dosage*
  • Hydrazines / adverse effects
  • Hydrazines / pharmacokinetics*
  • Hyponatremia / chemically induced
  • Hyponatremia / metabolism
  • Hyponatremia / pathology
  • Lymphoma, Non-Hodgkin / drug therapy*
  • Lymphoma, Non-Hodgkin / metabolism*
  • Lymphoma, Non-Hodgkin / pathology
  • Male
  • Middle Aged
  • Neoplasm Proteins / metabolism
  • Neutropenia / chemically induced
  • Neutropenia / metabolism
  • Neutropenia / pathology
  • Thrombocytopenia / chemically induced
  • Thrombocytopenia / metabolism
  • Thrombocytopenia / pathology
  • Triazoles / administration & dosage*
  • Triazoles / adverse effects
  • Triazoles / pharmacokinetics*

Substances

  • Hydrazines
  • Neoplasm Proteins
  • Triazoles
  • selinexor

Associated data

  • ClinicalTrials.gov/NCT01607892
  • ClinicalTrials.gov/NCT01607892