Recent thymic emigrants, T regulatory cells, and BAFF level in children with X-linked agammaglobulinaemia in association with chronic respiratory disease

Allergol Immunopathol (Madr). 2018 Jan-Feb;46(1):58-66. doi: 10.1016/j.aller.2017.01.011. Epub 2017 May 4.

Abstract

Background: X-linked agammaglobulinaemia (XLA) is a genetic disorder affecting B cell maturation, which is characterised by a low number of B cells, agammaglobulinaemia and increased susceptibility to a variety of bacterial infections. This study was performed to assess T cell subpopulations in a group of children with XLA in association with chronic respiratory disease (CRD).

Methods: Numbers of T cell subpopulations (CD3+, CD4+, CD8+, CD3+DR+, naïve, memory, recent thymic emigrants (RTE), regulatory T cells, follicular T helpers) were measured by eight-colour flow cytometry in 22 XLA patients and 50 controls. BAFF level was measured by ELISA.

Results: XLA patients with CRD had a significantly lower percentage of RTE numbers and Tregs, while significantly higher absolute counts of lymphocytes, CD3+, CD8+, CD3+DR+ and CD4+CD45RO+ T cells were detected as compared with healthy controls. In patients with XLA without CRD, the number of follicular T helper cells was altered significantly (percentage and absolute), as compared with healthy controls. Additionally, they had significantly higher counts (percentage and absolute) of CD4+CD45RA+ cells and lower percentage of CD4+CD45RO+ cells in comparison with healthy controls.

Conclusions: Our study affords new information concerning CRD and T cell subsets that differentiate or are maintained in the absence of B cells in children with XLA. T cell's homeostasis depends on the presence of chronic respiratory disease that may be caused by the delay in diagnosis.

Keywords: BAFF; Chronic lung infections; Chronic sinusitis; T cells; X-linked agammaglobulinaemia.

MeSH terms

  • Adolescent
  • Agammaglobulinemia / complications
  • Agammaglobulinemia / immunology*
  • B-Cell Activating Factor / metabolism*
  • Bronchitis / complications
  • Bronchitis / immunology*
  • Cell Separation
  • Child
  • Child, Preschool
  • Chronic Disease
  • Female
  • Flow Cytometry
  • Genetic Diseases, X-Linked / complications
  • Genetic Diseases, X-Linked / immunology*
  • Humans
  • Immunologic Memory
  • Immunophenotyping
  • Male
  • Sinusitis / complications
  • Sinusitis / immunology*
  • T-Lymphocyte Subsets / immunology*
  • T-Lymphocytes, Regulatory / immunology*
  • Thymocytes / immunology*

Substances

  • B-Cell Activating Factor
  • TNFSF13B protein, human

Supplementary concepts

  • Bruton type agammaglobulinemia