Hypoxia-inducible factor 1 alpha is a poor prognostic factor and potential therapeutic target in malignant peripheral nerve sheath tumor

PLoS One. 2017 May 30;12(5):e0178064. doi: 10.1371/journal.pone.0178064. eCollection 2017.

Abstract

Background: Malignant peripheral nerve sheath tumor (MPNST) is a rare soft tissue sarcoma with poor prognosis. Hypoxia-inducible factor 1 (HIF-1) plays a crucial role in the cellular response to hypoxia and regulates the expression of multiple genes involved in tumor progression in various cancers. However, the importance of the expression of HIF-1α in MPNSTs is unclear.

Methods: The expression of HIF-1α was examined immunohistochemically in 82 MPNST specimens. Cell culture assays of human MPNST cells under normoxic and hypoxic conditions were used to evaluate the impact of anti-HIF-1α-specific siRNA inhibition on cell survival. A screening kit was employed to identify small molecules that inhibited HIF-1α.

Results: The nuclear expression of HIF-1α was positive in 75.6% of MPNST samples (62/82 cases). Positivity for HIF-1α was a significant poor prognostic factor both in univariate (P = 0.048) and multivariate (P ≤ 0.0001) analyses. HIF-1α knockdown abrogated MPNST cell growth, inducing apoptosis. Finally, chetomin, an inhibitor of HIF-1α, effectively inhibited the growth of MPNST cells and induced their apoptosis.

Conclusion: Inhibition of HIF-1α signaling is a potential treatment option for MPNSTs.

MeSH terms

  • Cell Line, Tumor
  • Cell Proliferation
  • Female
  • Humans
  • Hypoxia-Inducible Factor 1, alpha Subunit / genetics
  • Hypoxia-Inducible Factor 1, alpha Subunit / metabolism*
  • Male
  • Middle Aged
  • Neurilemmoma / metabolism*
  • Neurilemmoma / pathology
  • Neurilemmoma / therapy
  • Oxygen / metabolism
  • Polymerase Chain Reaction
  • Prognosis
  • RNA, Small Interfering / genetics

Substances

  • Hypoxia-Inducible Factor 1, alpha Subunit
  • RNA, Small Interfering
  • Oxygen

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