Trans-ancestry Fine Mapping and Molecular Assays Identify Regulatory Variants at the ANGPTL8 HDL-C GWAS Locus

G3 (Bethesda). 2017 Sep 7;7(9):3217-3227. doi: 10.1534/g3.117.300088.

Abstract

Recent genome-wide association studies (GWAS) have identified variants associated with high-density lipoprotein cholesterol (HDL-C) located in or near the ANGPTL8 gene. Given the extensive sharing of GWAS loci across populations, we hypothesized that at least one shared variant at this locus affects HDL-C. The HDL-C-associated variants are coincident with expression quantitative trait loci for ANGPTL8 and DOCK6 in subcutaneous adipose tissue; however, only ANGPTL8 expression levels are associated with HDL-C levels. We identified a 400-bp promoter region of ANGPTL8 and enhancer regions within 5 kb that contribute to regulating expression in liver and adipose. To identify variants functionally responsible for the HDL-C association, we performed fine-mapping analyses and selected 13 candidate variants that overlap putative regulatory regions to test for allelic differences in regulatory function. Of these variants, rs12463177-G increased transcriptional activity (1.5-fold, P = 0.004) and showed differential protein binding. Six additional variants (rs17699089, rs200788077, rs56322906, rs3760782, rs737337, and rs3745683) showed evidence of allelic differences in transcriptional activity and/or protein binding. Taken together, these data suggest a regulatory mechanism at the ANGPTL8 HDL-C GWAS locus involving tissue-selective expression and at least one functional variant.

Keywords: Cholesterol; Complex genetic traits; Gene Expression; Genetics; Transcription.

MeSH terms

  • Aged
  • Alleles
  • Angiopoietin-Like Protein 8
  • Angiopoietin-like Proteins / genetics*
  • Animals
  • Cell Line
  • Cholesterol, HDL / genetics*
  • Chromosome Mapping*
  • Enhancer Elements, Genetic
  • Gene Expression
  • Genes, Reporter
  • Genetic Association Studies
  • Genetic Variation*
  • Genome-Wide Association Study*
  • Haplotypes
  • Humans
  • Male
  • Metabolic Syndrome / epidemiology
  • Metabolic Syndrome / genetics
  • Mice
  • Middle Aged
  • Organ Specificity / genetics
  • Peptide Hormones / genetics*
  • Polymorphism, Single Nucleotide
  • Promoter Regions, Genetic
  • Quantitative Trait Loci*
  • Quantitative Trait, Heritable
  • Regulatory Sequences, Nucleic Acid*
  • Subcutaneous Fat / metabolism

Substances

  • ANGPTL8 protein, human
  • Angiopoietin-Like Protein 8
  • Angiopoietin-like Proteins
  • Cholesterol, HDL
  • Peptide Hormones