Sarcoidosis with Takayasu arteritis: a model of overlapping granulomatosis. A report of seven cases and literature review

Int J Rheum Dis. 2018 Mar;21(3):740-745. doi: 10.1111/1756-185X.13137. Epub 2017 Aug 8.

Abstract

Objective: To describe the features of exceptional coexisting Takayasu arteritis (TA) and sarcoidosis, two conditions of unknown cause associated with a common immunologic pattern.

Methods: We report seven cases of concomitant sarcoidosis-Takayasu or Takayasu-like vasculitis, observed in two referral centers between 1995 and 2015.

Results: All patients were female. The mean age at sarcoidosis diagnosis and TA diagnosis was 36 and 37 years, respectively. Sarcoidosis occurred in 86% of cases before or together with TA. Sarcoidosis always had a classic expression except for one renal localization. Sarcoidosis was not severe and mostly non-treated (86%). In all cases of TA, supra-aortic arteries were involved; in only two TA cases a more diffuse inflammatory arterial involvement was noted. In one case, Takayasu arteritis occurred despite immunosuppressive therapy given for sarcoidosis. All patients received for TA a treatment with corticosteroids associated with methotrexate (four cases), infliximab (one case) or tocilizumab (one case). After a mean follow-up of 89 months, TA always improved and no death was observed.

Conclusions: TA stands as pathology associated with sarcoidosis. TA occurred in three cases among 50. When sarcoidosis preceded TA, a recovery of sarcoidosis was achieved mostly without treatment. TA is a prognostic and therapeutic factor. Immunosuppressive treatment, including steroids, led to a good prognosis for TA as well as for sarcoidosis.

Keywords: Takayasu arteritis; sarcoidosis.

Publication types

  • Multicenter Study
  • Review

MeSH terms

  • Adult
  • Female
  • France
  • Granuloma / complications*
  • Granuloma / diagnosis
  • Granuloma / drug therapy
  • Granuloma / immunology
  • Humans
  • Immunosuppressive Agents / therapeutic use
  • Middle Aged
  • Remission Induction
  • Sarcoidosis / complications*
  • Sarcoidosis / diagnosis
  • Sarcoidosis / drug therapy
  • Sarcoidosis / immunology
  • Takayasu Arteritis / complications*
  • Takayasu Arteritis / diagnosis
  • Takayasu Arteritis / drug therapy
  • Takayasu Arteritis / immunology
  • Time Factors
  • Treatment Outcome
  • Young Adult

Substances

  • Immunosuppressive Agents