Molecular and clinical characterization of new patient with 1,08 Mb deletion in 10p15.3 region

Mol Cytogenet. 2017 Sep 7:10:34. doi: 10.1186/s13039-017-0336-2. eCollection 2017.

Abstract

Background: Three distinct contiguous gene deletion syndromes are located at 10p chromosomal region. The deletion, involving 10p15.3 region, has been characterized by (DeScipio et al., Am J Med Genet A 158A:2152-61, 2012). However, because of the variation in size of the described deletions and lack of knowledge about the involved genes, the correlation between genotypes and patients' phenotypes remains unknown.

Case presentation: We describe female patient with de novo 1,08 Mb deletion in 10p15.3 region, similar to the patient nr seven reported by (DeScipio et al., Am J Med Genet A 158A:2152-61, 2012) but with more severe clinical features. Our patient demonstrated speech and motor delay, dysmorphic features, brain abnormalities and Tetralogy of Fallot with pulmonary atresia.

Conclusions: This case shows the importance of collection of more patients with deletion in order to obtain a more precise physical map of 10p region.

Keywords: 10p15.3 deletion; Intellectual disability; Language impairment.

Publication types

  • Case Reports