Comparison of the Frequency of Angioedema Attack, before and during Pregnancy, in a Patient with Type I Hereditary Angioedema

Intern Med. 2018 Mar 1;57(5):751-755. doi: 10.2169/internalmedicine.9407-17. Epub 2017 Nov 1.

Abstract

The patient was a 38-year-old Japanese woman who had been diagnosed with hereditary angioedema type I at 7 years of age based on her family history. She had undergone four pregnancies. She gave birth to a healthy baby girl after her first pregnancy and had reported few episodes of angioedema. However, she subsequently required abortions due to frequent angioedema episodes that occurred during her three subsequent pregnancies. Thus, our patient showed two clinical pregnancy courses. After treating her with C1-inhibitor concentrate, her symptoms of angioedema disappeared. The preventive use of C1 inhibitor concentrates should be considered in hereditary angioedema (HAE) patients with frequent angioedema attacks during pregnancy.

Keywords: C1 inhibitor; HAE; hereditary angioedema; pregnancy; replacement therapy.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Complement C1 Inhibitor Protein / therapeutic use*
  • Disease Progression
  • Female
  • Hereditary Angioedema Types I and II / complications*
  • Hereditary Angioedema Types I and II / drug therapy*
  • Humans
  • Pregnancy
  • Pregnancy Complications, Cardiovascular / drug therapy*
  • Recurrence

Substances

  • Complement C1 Inhibitor Protein
  • SERPING1 protein, human