Endothelial deletion of Ino80 disrupts coronary angiogenesis and causes congenital heart disease

Nat Commun. 2018 Jan 25;9(1):368. doi: 10.1038/s41467-017-02796-3.

Abstract

During development, the formation of a mature, well-functioning heart requires transformation of the ventricular wall from a loose trabecular network into a dense compact myocardium at mid-gestation. Failure to compact is associated in humans with congenital diseases such as left ventricular non-compaction (LVNC). The mechanisms regulating myocardial compaction are however still poorly understood. Here, we show that deletion of the Ino80 chromatin remodeler in vascular endothelial cells prevents ventricular compaction in the developing mouse heart. This correlates with defective coronary vascularization, and specific deletion of Ino80 in the two major coronary progenitor tissues-sinus venosus and endocardium-causes intermediate phenotypes. In vitro, endothelial cells promote myocardial expansion independently of blood flow in an Ino80-dependent manner. Ino80 deletion increases the expression of E2F-activated genes and endothelial cell S-phase occupancy. Thus, Ino80 is essential for coronary angiogenesis and allows coronary vessels to support proper compaction of the heart wall.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Research Support, U.S. Gov't, Non-P.H.S.

MeSH terms

  • ATPases Associated with Diverse Cellular Activities
  • Adenosine Triphosphatases / genetics
  • Adenosine Triphosphatases / metabolism*
  • Animals
  • Coronary Vessels / metabolism
  • DNA Helicases / genetics
  • DNA Helicases / metabolism
  • DNA-Binding Proteins
  • Endocardium / metabolism
  • Endocardium / pathology
  • Endothelial Cells / enzymology
  • Endothelial Cells / metabolism
  • Endothelium, Vascular / metabolism*
  • Endothelium, Vascular / pathology
  • Heart Defects, Congenital / genetics
  • Heart Defects, Congenital / metabolism*
  • Heart Ventricles / metabolism
  • Heart Ventricles / pathology
  • Humans
  • Mice, Knockout
  • Mice, Transgenic
  • Myocardium / metabolism
  • Myocardium / pathology
  • Neovascularization, Pathologic / genetics
  • Neovascularization, Pathologic / metabolism*

Substances

  • DNA-Binding Proteins
  • Adenosine Triphosphatases
  • ATPases Associated with Diverse Cellular Activities
  • DNA Helicases
  • INO80 protein, mouse