Emphysematous change with scleroderma-associated interstitial lung disease: the potential contribution of vasculopathy?

BMC Pulm Med. 2018 Jan 30;18(1):25. doi: 10.1186/s12890-018-0591-y.

Abstract

Background: Pulmonary emphysema combined with systemic sclerosis (SSc)-associated interstitial lung disease (ILD) occurs more often in smokers but also in never-smokers. This study aimed to describe a new finding characterized by peculiar emphysematous change with SSc-associated ILD (SSc-ILD).

Methods: We conducted a retrospective review of 21 consecutive patients with SSc-ILD diagnosed by surgical lung biopsy and focused on the radio-pathological correlation of the emphysematous change.

Results: Pathological pulmonary emphysema (p-PE) with SSc-ILD was the predominant complication in 16 patients (76.2%) with/without a smoking history, of whom 62.5% were never-smokers. A low attenuation area (LAA) within interstitial abnormality on high-resolution computed tomography (HRCT) was present in 31.3%. Diffusing capacity of the lung for carbon monoxide (DLCO) was lower, disease extent on HRCT higher, and intimal/medial thickening in muscular pulmonary arteries more common in the patients with p-PE with SSc-ILD. However, forced vital capacity (FVC) was well preserved regardless of whether p-PE was observed. Most SSc-ILD patients had pulmonary microvasculature changes in arterioles (90.5%), venules (85.7%), and interlobular veins (81.0%).

Conclusions: Pulmonary emphysematous changes (LAA within interstitial abnormalities on HRCT and destruction of fibrously thickened alveolar walls) are specific and novel radio-pathological features of SSc-ILD. Peripheral vasculopathy may help to destroy the fibrously thickened alveolar walls, resulting in emphysematous change in SSc-ILD.

Keywords: Emphysematous change; Systemic sclerosis; Vasculopathy.

MeSH terms

  • Aged
  • Carbon Monoxide
  • Female
  • Forced Expiratory Volume
  • Humans
  • Lung / blood supply*
  • Lung / diagnostic imaging
  • Lung / pathology
  • Lung / physiopathology
  • Lung Diseases, Interstitial / diagnostic imaging*
  • Lung Diseases, Interstitial / etiology
  • Lung Diseases, Interstitial / pathology
  • Lung Diseases, Interstitial / physiopathology
  • Male
  • Microvessels / pathology*
  • Middle Aged
  • Pulmonary Artery / pathology*
  • Pulmonary Diffusing Capacity
  • Pulmonary Emphysema / diagnostic imaging*
  • Pulmonary Emphysema / etiology
  • Pulmonary Emphysema / pathology
  • Pulmonary Emphysema / physiopathology
  • Retrospective Studies
  • Scleroderma, Systemic / complications*
  • Tomography, X-Ray Computed
  • Tunica Intima / pathology
  • Vascular Diseases / pathology
  • Vital Capacity

Substances

  • Carbon Monoxide