Ocular neuromyotonia

Pract Neurol. 2018 Oct;18(5):389-390. doi: 10.1136/practneurol-2017-001866. Epub 2018 Feb 21.

Abstract

Ocular neuromyotonia is a rare, albeit treatable, ocular motor disorder, characterised by recurrent brief episodes of diplopia due to tonic extraocular muscle contraction. Ephaptic transmission in a chronically damaged ocular motor nerve is the possible underlying mechanism. It usually improves with carbamazepine. A 53-year-old woman presented with a 4-month history of recurrent episodes of binocular vertical diplopia (up to 40/day), either spontaneously or after sustained downward gaze. Between episodes she had a mild left fourth nerve palsy. Sustained downward gaze consistently triggered downward left eye tonic deviation, lasting around 1 min. MR scan of the brain was normal. She improved on starting carbamazepine but developed a rash that necessitated stopping the drug. Switching to lacosamide controlled her symptoms.

Keywords: diplopia; lacosamide; ocular neuromyotonia; trochear nerve.

Publication types

  • Case Reports

MeSH terms

  • Female
  • Fixation, Ocular / physiology
  • Humans
  • Isaacs Syndrome / complications*
  • Middle Aged
  • Ocular Motility Disorders / complications*