Spindle cell rhabdomyosarcoma of bone with FUS-TFCP2 fusion: confirmation of a very recently described rhabdomyosarcoma subtype

Histopathology. 2018 Sep;73(3):514-520. doi: 10.1111/his.13649. Epub 2018 Jun 29.

Abstract

Aims: Rhabdomyosarcomas of bone are extremely rare, with fewer than 10 reported cases. A very rare subtype of spindle cell/sclerosing rhabdomyosarcoma harbouring a FUS-TFCP2 fusion and involving both soft tissue and bone locations has been reported very recently. We report only the fourth case of this unusual, clinically aggressive rhabdomyosarcoma.

Material and results: A previously well 72-year-old male presented with a destructive lesion of the mandible. Morphological and immunohistochemical study of a needle biopsy and the subsequent resection showed a spindle cell rhabdomyosarcoma. RNA-seq, RT-PCR and FISH confirmed the presence of the FUS-TFCP2 fusion.

Conclusions: Spindle cell rhabdomyosarcomas carrying the FUS-TFCP2 fusion are very rare rhabdomyosarcoma variants with osseous predilection. The classification and differential diagnosis of this unusual molecular variant of spindle cell/sclerosing rhabdomyosarcoma are discussed.

Keywords: FUS; TFCP2; RNA-seq; fluorescence in-situ hybridisation; rhabdomyosarcoma; sclerosing; spindle cell.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • DNA-Binding Proteins / genetics*
  • Humans
  • Male
  • Mandibular Neoplasms / genetics*
  • Mandibular Neoplasms / pathology
  • Oncogene Proteins, Fusion / genetics*
  • RNA-Binding Protein FUS / genetics*
  • Rhabdomyosarcoma / genetics*
  • Rhabdomyosarcoma / pathology
  • Transcription Factors / genetics*

Substances

  • DNA-Binding Proteins
  • FUS protein, human
  • Oncogene Proteins, Fusion
  • RNA-Binding Protein FUS
  • TFCP2 protein, human
  • Transcription Factors